Is tuberous sclerosis complex-associated autism a preventable and treatable disorder?

World J Pediatr. 2024 Jan;20(1):40-53. doi: 10.1007/s12519-023-00762-2. Epub 2023 Oct 25.

Abstract

Background: Tuberous sclerosis complex (TSC) is a genetic disorder caused by inactivating mutations in the TSC1 and TSC2 genes, causing overactivation of the mechanistic (previously referred to as mammalian) target of rapamycin (mTOR) signaling pathway in fetal life. The mTOR pathway plays a crucial role in several brain processes leading to TSC-related epilepsy, intellectual disability, and autism spectrum disorder (ASD). Pre-natal or early post-natal diagnosis of TSC is now possible in a growing number of pre-symptomatic infants.

Data sources: We searched PubMed for peer-reviewed publications published between January 2010 and April 2023 with the terms "tuberous sclerosis", "autism", or "autism spectrum disorder"," animal models", "preclinical studies", "neurobiology", and "treatment".

Results: Prospective studies have highlighted that developmental trajectories in TSC infants who were later diagnosed with ASD already show motor, visual and social communication skills in the first year of life delays. Reliable genetic, cellular, electroencephalography and magnetic resonance imaging biomarkers can identify pre-symptomatic TSC infants at high risk for having autism and epilepsy.

Conclusions: Preventing epilepsy or improving therapy for seizures associated with prompt and tailored treatment strategies for autism in a sensitive developmental time window could have the potential to mitigate autistic symptoms in infants with TSC.

Keywords: Animal model; Autism spectrum disorders; Developmental and epileptic encephalopathy; Mechanisms; Risk; Tuberos sclerosis complex; mTOR.

Publication types

  • Review

MeSH terms

  • Animals
  • Autism Spectrum Disorder* / diagnosis
  • Autism Spectrum Disorder* / etiology
  • Autism Spectrum Disorder* / prevention & control
  • Autistic Disorder* / diagnosis
  • Autistic Disorder* / etiology
  • Autistic Disorder* / therapy
  • Epilepsy* / diagnosis
  • Epilepsy* / etiology
  • Epilepsy* / prevention & control
  • Humans
  • Infant
  • Mammals / metabolism
  • Prospective Studies
  • TOR Serine-Threonine Kinases / metabolism
  • Tuberous Sclerosis* / complications
  • Tuberous Sclerosis* / diagnosis
  • Tuberous Sclerosis* / genetics

Substances

  • TOR Serine-Threonine Kinases