Long-term Elevation of Complement Factors in Cerebrospinal Fluid of Patients With Borna Disease Virus 1 Encephalitis

J Infect Dis. 2024 Oct 16;230(4):e943-e953. doi: 10.1093/infdis/jiae183.

Abstract

Background: Borna disease virus 1 (BoDV-1) causes rare but severe zoonotic infections in humans, presenting as encephalitis. The case-fatality risk is very high and no effective countermeasures have been established so far. An immunopathology is presumed, while data on immune responses in humans are limited. Evidence of a role of the complement system in various neurological disorders and in viral infections of the central nervous system is increasing and specific inhibitors are available as therapeutic options.

Methods: In this study, we investigated factors of the complement system in the cerebrospinal fluid (CSF) of patients with BoDV-1 infections (n = 17) in comparison to noninflammatory control CSF samples (n = 11), using a bead-based multiplex assay. In addition, immunohistochemistry was performed using postmortem brain tissue samples.

Results: We found an intrathecal elevation of complement factors of all complement pathways and an active cascade during human BoDV-1 infections. The increase of certain complement factors such as C1q was persistent, and C3 complement deposits were detected in postmortem brain sections. Intrathecal complement levels were negatively correlated with survival.

Conclusions: Further investigations are warranted to clarify whether targeting the complement cascade by specific inhibitors might be beneficial for patients suffering from severe BoDV-1 encephalitis.

Keywords: BoDV-1; biomarkers; complement system; immunopathogenesis; zoonosis.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Borna Disease* / cerebrospinal fluid
  • Borna Disease* / immunology
  • Borna Disease* / virology
  • Borna disease virus* / immunology
  • Brain / immunology
  • Brain / pathology
  • Brain / virology
  • Child
  • Child, Preschool
  • Complement System Proteins / cerebrospinal fluid
  • Complement System Proteins / immunology
  • Complement System Proteins / metabolism
  • Female
  • Humans
  • Infant
  • Male
  • Middle Aged
  • Young Adult

Substances

  • Complement System Proteins