Portal hypertension and its prognostic implications in patients with Wilson's disease

Aliment Pharmacol Ther. 2024 Jul;60(2):257-266. doi: 10.1111/apt.18060. Epub 2024 May 26.

Abstract

Background and aims: Wilson's disease may progress to cirrhosis and clinically significant portal hypertension (CSPH). We aimed to assess the prevalence and prognostic impact of CSPH-related features on hepatic decompensation and transplant-free survival in patients with Wilson's disease.

Methods and results: About 137 patients with Wilson's disease (Leipzig score ≥4), followed for a median observation period of 9.0 (3.9-17.7) years at the Vienna General Hospital, were included in this retrospective study. Overall, 49 (35.8%) developed features of CSPH: 14 (10.2%) varices, 40 (29.2%) splenomegaly, 20 (14.6%) ascites, 18 (13.1%) hepatic encephalopathy and 3 (2.2%) experienced acute variceal bleeding. Overall, 8 (5.8%) patients died, including three deaths caused by CSPH-related complications. Within 10 years, compensated patients with features of CSPH developed more decompensation events (8.3% vs. 1.5% in patients without CSPH, p = 0.3) and had worse transplant-free-survival (91.7% vs. 98.6%), which further declined in patients with hepatic decompensation (26.7%, log-rank: p < 0.0001). Patients with liver stiffness <15 kPa and normal platelets (≥150 G/L) were less likely to decompensate within 10 years (2.6% vs. 8.4%, p = 0.002) and had a better 10-year transplant-free-survival (97.7% vs. 83.9%, p = 0.006).

Conclusions: Patients with Wilson's disease developing features of CSPH are at an increased risk for hepatic decompensation and liver-related mortality, warranting for regular screening and timely initiation of effective CSPH-directed treatments.

MeSH terms

  • Adolescent
  • Adult
  • Austria / epidemiology
  • Child
  • Disease Progression
  • Esophageal and Gastric Varices / etiology
  • Female
  • Gastrointestinal Hemorrhage / etiology
  • Hepatic Encephalopathy / etiology
  • Hepatolenticular Degeneration* / complications
  • Hepatolenticular Degeneration* / mortality
  • Hepatolenticular Degeneration* / physiopathology
  • Humans
  • Hypertension, Portal* / complications
  • Hypertension, Portal* / etiology
  • Hypertension, Portal* / mortality
  • Liver Cirrhosis / complications
  • Liver Cirrhosis / mortality
  • Liver Transplantation
  • Male
  • Middle Aged
  • Prognosis
  • Retrospective Studies
  • Young Adult