Juvenile Xanthogranuloma of the Head and Neck: Imaging Findings in 11 Cases

J Pediatr Hematol Oncol. 2024 Aug 1;46(6):e368-e380. doi: 10.1097/MPH.0000000000002872. Epub 2024 Jun 3.

Abstract

Background: Juvenile Xanthogranuloma (JXG) is a non-Langerhans cell histiocytosis, occurring mainly in infancy. With an extracutaneous lesion, its diagnosis is difficult, because of a wide clinical spectrum. Here we demonstrate and characterize imaging features of 11 patients with JXG of the head and neck in various locations.

Material and methods: We recorded clinical data and reviewed all imaging studies of 11 patients with JXG of the head and neck. Ultrasonography (US) alone was performed in 1 patient; MRI alone in 6 patients; US and MRI in 1 patient; and US, CT, and MRI in 3 patients. We evaluated the following characteristics in all studies: location and number of lesions, echogenicity and vascularization on US, density on CT, signal intensity on T 1 - and T 2 -weighted images, ADC and enhancement on MRI, and tumor boundaries and bone involvement.

Results: Lesions were well-defined in 9 cases, and bone erosion was present in 2. On US, lesions were hypoechoic or hyperechoic and with or without vascularization. On CT, lesions were hyper-dense, with no calcification. On MRI, lesions were mildly hyper-intense or iso-intense on T 1 -weighted images in 8 of 9 patients, hypo-intense on T2-weighted images in 7 of 10, low ADC in 7 of 9, and enhancement in 7 of 7.

Conclusions: The diagnosis of extra cutaneous JXG may be proposed, with the following suggestive criteria: age < 1 year, well-defined lesion, mild hyper-intensity on T 1 -weighted images, hypo-intensity on T 2 -weighted images, low ADC, enhancement, and possible adjacent bone involvement.

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Female
  • Head* / diagnostic imaging
  • Head* / pathology
  • Humans
  • Infant
  • Magnetic Resonance Imaging* / methods
  • Male
  • Neck / diagnostic imaging
  • Neck / pathology
  • Tomography, X-Ray Computed
  • Ultrasonography* / methods
  • Xanthogranuloma, Juvenile* / diagnostic imaging
  • Xanthogranuloma, Juvenile* / pathology