A novel SPAST gene splicing variant (c.1617-2A>C) in a heterozygous carrier with hereditary spastic paraplegia

eNeurologicalSci. 2024 May 29:35:100506. doi: 10.1016/j.ensci.2024.100506. eCollection 2024 Jun.

Abstract

Hereditary spastic paraplegia (HSP) is a group of genetically heterogenous neurodegenerative disorders characterized by progressive spasticity and weakness of lower limbs. We report a novel splicing variant (c.1617-2A>C) of the SPAST gene in a heterozygous carrier from an Italian family with autosomal dominant HSP. The case study describes a pure form of spastic paraparesis with the cardinal clinical features of SPG4. The novel variant affects a canonical splice site and is likely to disrupt RNA splicing. We conclude that the c.1617-2A>C substitution is a null variant, which could be classified as pathogenic; its penetrance should be further investigated.

Keywords: Genetic risk factor, splice variant; Genotype; HSP; Hereditary spastic paraplegia; SPAST; SPG4; Spastin; VUS.

Publication types

  • Case Reports