Long-term durability between parent and child patient-reported outcomes in eosinophilic esophagitis

J Allergy Clin Immunol. 2024 Nov;154(5):1232-1240.e12. doi: 10.1016/j.jaci.2024.07.011. Epub 2024 Jul 25.

Abstract

Background: Because young children cannot self-report symptoms, there is a need for parent surrogate reports. Although early work suggested parent-child alignment for eosinophil esophagitis (EoE) patient-reported outcomes (PROs), the longitudinal alignment is unclear.

Objective: We sought to assess the agreement and longitudinal stability of PROs between children with EoE and their parents.

Methods: A total of 292 parent-child respondents completed 723 questionnaires over 5 years in an observational trial in the Consortium of Eosinophilic Gastrointestinal Disease Researchers. The change in and agreement between parent and child Pediatric Eosinophilic Esophagitis Symptom Score version 2 (PEESSv2.0) and Pediatric Quality of Life Eosinophilic Esophagitis Module (PedsQL-EoE) PROs over time were assessed using Pearson correlation and Bland-Altman analyses. Clinical factors influencing PROs and their agreement were evaluated using linear mixed models.

Results: The cohort had a median disease duration equaling 3.7 years and was predominantly male (73.6%) and White (85.3%). Child and parent PEESSv2.0 response groups were identified and were stable over time. There was strong correlation between child and parent reports (PEESSv2.0, 0.83;PedsQL-EoE, 0.74), with minimal pairwise differences for symptoms. Longitudinally, parent-reported PedsQL-EoE scores were stable (P ≥ .32), whereas child-reported PedsQL-EoE scores improved (P = .026). A larger difference in parent and child PedsQL-EoE reports was associated with younger age (P < .001), and differences were driven by psychosocial PRO domains.

Conclusions: There is strong longitudinal alignment between child and parent reports using EoE PROs. These data provide evidence that parent report is a stable proxy for objective EoE symptoms in their children.

Keywords: Pediatric; clinical trial readiness; eosinophilic esophagitis; food allergy; multicenter; patient-reported outcomes; quality of life.

Publication types

  • Observational Study

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Eosinophilic Esophagitis* / therapy
  • Female
  • Humans
  • Longitudinal Studies
  • Male
  • Parents* / psychology
  • Patient Reported Outcome Measures*
  • Quality of Life*
  • Self Report
  • Surveys and Questionnaires