Therapeutic targeting of RNA for neurological and neuromuscular disease

Genes Dev. 2024 Sep 19;38(15-16):698-717. doi: 10.1101/gad.351612.124.

Abstract

Neurological and neuromuscular diseases resulting from familial, sporadic, or de novo mutations have devasting personal, familial, and societal impacts. As the initial product of DNA transcription, RNA transcripts and their associated ribonucleoprotein complexes provide attractive targets for modulation by increasing wild-type or blocking mutant allele expression, thus relieving downstream pathological consequences. Therefore, it is unsurprising that many existing and under-development therapeutics have focused on targeting disease-associated RNA transcripts as a frontline drug strategy for these genetic disorders. This review focuses on the current range of RNA targeting modalities using examples of both dominant and recessive neurological and neuromuscular diseases.

Keywords: RNA; RNP; neurological disease; neuromuscular disease; therapeutics.

Publication types

  • Review

MeSH terms

  • Animals
  • Humans
  • Molecular Targeted Therapy / methods
  • Nervous System Diseases* / drug therapy
  • Nervous System Diseases* / genetics
  • Nervous System Diseases* / therapy
  • Neuromuscular Diseases* / drug therapy
  • Neuromuscular Diseases* / genetics
  • Neuromuscular Diseases* / therapy
  • RNA* / genetics
  • RNA* / metabolism

Substances

  • RNA