Anti-Ceramide ScFv Prophylaxis for First Responders to a Limited Nuclear Attack

Cell Physiol Biochem. 2024 Aug 21;58(4):418-430. doi: 10.33594/000000721.

Abstract

Background/aims: After 9/11, multiple government agencies instituted programs aimed at developing medical radiation countermeasures (MRCs) for two syndromes lethal within weeks of a limited nuclear attack; the hematopoietic-acute radiation syndrome (H-ARS) and the higher-dose gastrointestinal-acute radiation syndrome (GI-ARS). While re-purposing drugs that enhance marrow repopulation treats H-ARS, no mitigator protects GI tract.

Methods: We recently reported anti-ceramide 6B5 single-chain variable fragment (scFv) pre-treatment abrogates ongoing small intestinal endothelial apoptosis to rescue Lgr5+ stem cells, preventing GI-ARS lethality in C57B/L6J mice. Here, with US Department of Defense support, we provide evidence that humanized anti-ceramide scFv (CX-01) is a promising prophylactic MRC for first responders, who risk exposure upon entering a radiation-contaminated site.

Results: CX-01, when delivered up to 90 min before irradiation, is highly-effective in preventing small intestinal endothelial apoptosis in mice and lethality in both sexes. Unexpectedly, females require an ~2-fold higher CX-01 dose than males for full protection. CX-01 is effective subcutaneously and intramuscularly, a property critical for battlefield use. Increasing the maximally-effective dose 5-fold does not extend duration of bioeffectiveness.

Conclusion: While CX-01 prevents GI-ARS lethality, structural modification to extend half-life may be necessary to optimize first responder prophylaxis.

Keywords: Gi-ARS ; ScFv ; Endothelial cells ; ASMase ; Ceramide.

MeSH terms

  • Acute Radiation Syndrome / drug therapy
  • Acute Radiation Syndrome / pathology
  • Acute Radiation Syndrome / prevention & control
  • Animals
  • Apoptosis* / drug effects
  • Ceramides* / metabolism
  • Female
  • Humans
  • Intestine, Small / drug effects
  • Intestine, Small / pathology
  • Intestine, Small / radiation effects
  • Male
  • Mice
  • Mice, Inbred C57BL*
  • Nuclear Weapons
  • Radiation-Protective Agents / pharmacology
  • Radiation-Protective Agents / therapeutic use
  • Single-Chain Antibodies* / immunology

Substances

  • Single-Chain Antibodies
  • Ceramides
  • Radiation-Protective Agents