Tropomyosin 1 deficiency facilitates cell state transitions and enhances hemogenic endothelial cell specification during hematopoiesis

Stem Cell Reports. 2024 Sep 10;19(9):1264-1276. doi: 10.1016/j.stemcr.2024.08.001. Epub 2024 Aug 29.

Abstract

Tropomyosins coat actin filaments to impact actin-related signaling and cell morphogenesis. Genome-wide association studies have linked Tropomyosin 1 (TPM1) with human blood trait variation. TPM1 has been shown to regulate blood cell formation in vitro, but it remains unclear how or when TPM1 affects hematopoiesis. Using gene-edited induced pluripotent stem cell (iPSC) model systems, we found that TPM1 knockout augmented developmental cell state transitions and key signaling pathways, including tumor necrosis factor alpha (TNF-α) signaling, to promote hemogenic endothelial (HE) cell specification and hematopoietic progenitor cell (HPC) production. Single-cell analyses revealed decreased TPM1 expression during human HE specification, suggesting that TPM1 regulated in vivo hematopoiesis via similar mechanisms. Analyses of a TPM1 gene trap mouse model showed that TPM1 deficiency enhanced HE formation during embryogenesis, without increasing the number of hematopoietic stem cells. These findings illuminate novel effects of TPM1 on developmental hematopoiesis.

Keywords: hematopoiesis; hemogenic endothelium; induced pluripotent stem cell; mouse model; tropomyosin 1.

MeSH terms

  • Animals
  • Cell Differentiation* / genetics
  • Endothelial Cells / cytology
  • Endothelial Cells / metabolism
  • Hemangioblasts / cytology
  • Hemangioblasts / metabolism
  • Hematopoiesis* / genetics
  • Hematopoietic Stem Cells* / cytology
  • Hematopoietic Stem Cells* / metabolism
  • Humans
  • Induced Pluripotent Stem Cells / cytology
  • Induced Pluripotent Stem Cells / metabolism
  • Mice
  • Signal Transduction
  • Tropomyosin* / genetics
  • Tropomyosin* / metabolism
  • Tumor Necrosis Factor-alpha / metabolism

Substances

  • Tropomyosin
  • TPM1 protein, human
  • Tumor Necrosis Factor-alpha