MerlinS13 phosphorylation regulates meningioma Wnt signaling and magnetic resonance imaging features

Nat Commun. 2024 Sep 9;15(1):7873. doi: 10.1038/s41467-024-52284-8.

Abstract

Meningiomas are associated with inactivation of NF2/Merlin, but approximately one-third of meningiomas with favorable clinical outcomes retain Merlin expression. Biochemical mechanisms underlying Merlin-intact meningioma growth are incompletely understood, and non-invasive biomarkers that may be used to guide treatment de-escalation or imaging surveillance are lacking. Here, we use single-cell RNA sequencing, proximity-labeling proteomic mass spectrometry, mechanistic and functional approaches, and magnetic resonance imaging (MRI) across meningioma xenografts and patients to define biochemical mechanisms and an imaging biomarker that underlie Merlin-intact meningiomas. We find Merlin serine 13 (S13) dephosphorylation drives meningioma Wnt signaling and tumor growth by attenuating inhibitory interactions with β-catenin and activating the Wnt pathway. MRI analyses show Merlin-intact meningiomas with S13 phosphorylation and favorable clinical outcomes are associated with high apparent diffusion coefficient (ADC). These results define mechanisms underlying a potential imaging biomarker that could be used to guide treatment de-escalation or imaging surveillance for patients with Merlin-intact meningiomas.

MeSH terms

  • Animals
  • Biomarkers, Tumor / genetics
  • Biomarkers, Tumor / metabolism
  • Cell Line, Tumor
  • Female
  • Humans
  • Magnetic Resonance Imaging* / methods
  • Male
  • Meningeal Neoplasms* / diagnostic imaging
  • Meningeal Neoplasms* / genetics
  • Meningeal Neoplasms* / metabolism
  • Meningeal Neoplasms* / pathology
  • Meningioma* / diagnostic imaging
  • Meningioma* / genetics
  • Meningioma* / metabolism
  • Meningioma* / pathology
  • Mice
  • Neurofibromin 2* / genetics
  • Neurofibromin 2* / metabolism
  • Phosphorylation
  • Proteomics / methods
  • Serine / metabolism
  • Wnt Signaling Pathway*
  • beta Catenin / genetics
  • beta Catenin / metabolism

Substances

  • Neurofibromin 2
  • beta Catenin
  • Serine
  • Biomarkers, Tumor