DEK::AFF2 Fusion-Associated Squamous Cell Carcinoma: A Case Series with Literature Review on an Emerging and Challenging Entity

Head Neck Pathol. 2024 Sep 23;18(1):86. doi: 10.1007/s12105-024-01690-x.

Abstract

Purpose: DEK::AFF2 fusion-associated squamous cell carcinoma (DEK::AFF2 SCC), also reported in the literature as low-grade papillary sinonasal (Schneiderian) carcinoma (LGPSC), is a rare, primarily bland-appearing, but locally aggressive neoplasm. Morphologically, these tumors can closely resemble sinonasal papilloma (SP), especially on small or limited biopsy, often leading to misdiagnosis. DEK::AFF2 SCC is devoid of the underlying mutually exclusive EGFR or KRAS driver mutations of SP, suggesting it may represent a distinct unique entity.

Methods: In this study, we conducted a retrospective search of "unusual" SP reported either as atypical, dysplastic, or suspicious for malignant transformation at our institution in the last 13 years (2010-2023), to identify potential cases of DEK::AFF2 SCC.

Results: Of the 201 SP cases during this time period, 30 "unusual" SP cases were identified. On morphologic review of these 30 cases, 6 were worrisome for DEK::AFF2 SCC and were selected for AFF2 immunohistochemical stain (IHC), of which 3 cases were positive. All 3 AFF2 IHC positive cases were also positive for DEK::AFF2 fusion by fluorescence in situ hybridization (FISH), thereby, confirming IHC results.

Conclusions: This study highlights that AFF2 IHC can be an invaluable surrogate marker to FISH in identifying DEK::AFF2 SCC in challenging cases to avoid misdiagnosis. Detailed clinical and pathologic data were collected to gain a better understanding of this emerging challenging entity. A literature review was performed to enrich our knowledge of DEK::AFF2 SCC.

Keywords: DEK:AFF2 fusion; AFF2; DEK; Fluorescence in situ hybridization; Immunohistochemistry; Sinonasal carcinoma; Sinonasal papilloma.

Publication types

  • Review
  • Case Reports

MeSH terms

  • Adult
  • Aged
  • Biomarkers, Tumor / analysis
  • Biomarkers, Tumor / genetics
  • Carcinoma, Squamous Cell / diagnosis
  • Carcinoma, Squamous Cell / genetics
  • Carcinoma, Squamous Cell / pathology
  • Chromosomal Proteins, Non-Histone* / genetics
  • Female
  • Humans
  • Male
  • Middle Aged
  • Oncogene Proteins* / genetics
  • Oncogene Proteins, Fusion / genetics
  • Paranasal Sinus Neoplasms / genetics
  • Paranasal Sinus Neoplasms / pathology
  • Poly-ADP-Ribose Binding Proteins* / genetics
  • Retrospective Studies
  • Squamous Cell Carcinoma of Head and Neck / genetics
  • Squamous Cell Carcinoma of Head and Neck / pathology

Substances

  • DEK protein, human
  • Poly-ADP-Ribose Binding Proteins
  • Oncogene Proteins
  • Chromosomal Proteins, Non-Histone
  • Biomarkers, Tumor
  • Oncogene Proteins, Fusion