Case report: A case study of variant calling pipeline selection effect on the molecular diagnostics outcome

Front Oncol. 2024 Oct 31:14:1422811. doi: 10.3389/fonc.2024.1422811. eCollection 2024.

Abstract

Next-generation sequencing technologies have not only defined a breakthrough in medical genetics, but also been able to enter routine clinical practice to determine individual genetic susceptibilities. Modern technological developments are routinely introduced to genetic analysis overtaking the established approaches, potentially raising a number of challenges. To what extent is the advantage of new methodologies in synthetic metrics, such as precision and recall, more important than stability and reproducibility? Could differences in the technical protocol for calling variants be crucial to the diagnosis and, by extension, the patient's treatment strategy? A regulatory review process may delay the incorporation of potentially beneficial technologies, resulting in missed opportunities to make the right medical decisions. On the other hand, a blind adoption of new technologies based solely on synthetic metrics of precision and recall can lead to incorrect conclusions and adverse outcomes for the specific patient. Here, we use the example of a patient with a WHO-diagnosed desmoplastic/nodular SHH-medulloblastoma to explore how the choice of DNA variant search protocol affects the genetic diagnostics outcome.

Keywords: DeepVariant; HaplotypeCaller; SHH medulloblastoma; germline; pediatric oncology; undiagnosed cases; variant calling.

Publication types

  • Case Reports

Grants and funding

The author(s) declare financial support was received for the research, authorship, and/or publication of this article. RS, YD, SS, MK, AS, DM, and AL received support from the Ministry of Science and Higher Education of the Russian Federation under Agreement #075-15-2022-301. MA received support from the Nationwide Foundation Pediatric Innovation Fund.