Single-Cell RNA Sequencing of PBMCs Identified Junction Plakoglobin (JUP) as Stratification Biomarker for Endometriosis

Int J Mol Sci. 2024 Dec 5;25(23):13071. doi: 10.3390/ijms252313071.

Abstract

This study aimed to identify unique characteristics in the peripheral blood mononuclear cells (PBMCs) of endometriosis patients and develop a non-invasive early diagnostic tool. Using single-cell RNA sequencing (scRNA-seq), we constructed the first single-cell atlas of PBMCs from endometriosis patients based on 107,964 cells and 25,847 genes. Within CD16+ monocytes, we discovered JUP as a dysregulated gene. To assess its diagnostic potential, we measured peritoneal fluid (PF) and serum JUP levels in a large cohort of 199 patients including 20 women with ovarian cancer (OC). JUP was barely detectable in PF but was significantly elevated in the serum of patients with endometriosis and OC, with levels 1.33 and 2.34 times higher than controls, respectively. Additionally, JUP was found in conditioned culture media of CD14+/CD16+ monocytes aligning with our scRNA-seq data. Serum JUP levels correlated with endometriosis severity and endometrioma presence but were unaffected by dysmenorrhea, menstrual cycle, or adenomyosis. When combined with CA125 (cancer antigen 125) JUP enhanced the specificity of endometriosis diagnosis from 89.13% (CA125 measured alone) to 100%. While sensitivity remains a challenge at 19%, our results suggest that JUP's potential to enhance diagnostic accuracy warrants additional investigation. Furthermore, employing serum JUP as a stratification marker unlocked the potential to identify additional endometriosis-related genes, offering novel insights into disease pathogenesis.

Keywords: Junctional plakoglobin (JUP); adenomyosis; diagnostic biomarkers; endometriosis; peripheral blood mononuclear cells (PBMCs); single-cell RNA-sequencing (scRNA-seq).

MeSH terms

  • Adult
  • Ascitic Fluid / metabolism
  • Biomarkers* / blood
  • CA-125 Antigen / blood
  • CA-125 Antigen / genetics
  • CA-125 Antigen / metabolism
  • Endometriosis* / blood
  • Endometriosis* / diagnosis
  • Endometriosis* / genetics
  • Endometriosis* / metabolism
  • Female
  • Humans
  • Leukocytes, Mononuclear* / metabolism
  • Middle Aged
  • Monocytes / metabolism
  • Ovarian Neoplasms / blood
  • Ovarian Neoplasms / diagnosis
  • Ovarian Neoplasms / genetics
  • Ovarian Neoplasms / pathology
  • Receptors, IgG / genetics
  • Receptors, IgG / metabolism
  • Sequence Analysis, RNA
  • Single-Cell Analysis* / methods
  • gamma Catenin

Substances

  • Biomarkers
  • JUP protein, human
  • CA-125 Antigen
  • Receptors, IgG
  • gamma Catenin

Grants and funding

This study was funded by the Swiss National Science Foundation Kommission für Technologie und Innovation (Innosuisse Project n° 40967.1 IP-LS) as a joint project between Inselspital (Bern) and Scailyte AG (Basel).