Mapping of two genes encoding isoforms of the actin binding protein ABP-280, a dystrophin like protein, to Xq28 and to chromosome 7

Hum Mol Genet. 1993 Jun;2(6):761-6. doi: 10.1093/hmg/2.6.761.

Abstract

ABP-280 is a ubiquitous actin binding protein present in the cytoskeleton of many different cell types. ABP-280 was mapped to distal Xq28, 50-60 kb downstream of the Green Colour Pigment (GCP) genes. To establish if ABP-280 may be a candidate for one of the muscle disease localized by linkage analysis to distal Xq28 we looked for alternative forms of ABP-280 mRNA. Several different ABP-280 mRNAs were indeed identified: two are X-linked and are produced by alternative splicing of a small exon of 24 nucleotides. At least one additional gene encoding a RNA more than 70% identical to ABP-280 in the 1700 bp sequenced has also been found. It was mapped to chromosome 7. While both forms of the X-linked ABP-280 are ubiquitous, the gene on chromosome 7 is highly expressed only in skeletal muscle and heart. The two genes were therefore excellent candidates for the X-linked and for the autosomal dominant form of the Emery-Dreifuss Muscular Dystrophy (EDMD) both of which have been described. So far, however we were unable to demonstrate mutations in the coding region or affecting the alternative splicing of the X-linked form of ABP-280, in several patients studied, and we think that it is quite unlikely that this is the gene responsible for EDMD.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acid Sequence
  • Base Sequence
  • Carrier Proteins / genetics*
  • Chromosome Mapping
  • Chromosomes, Human, Pair 7*
  • Cloning, Molecular
  • Contractile Proteins / genetics*
  • DNA / genetics
  • Filamins
  • Genes*
  • HeLa Cells
  • Humans
  • Male
  • Microfilament Proteins / genetics*
  • Molecular Sequence Data
  • Muscle Proteins / genetics*
  • Muscular Dystrophies / classification
  • Muscular Dystrophies / genetics*
  • Myocardium / metabolism
  • Organ Specificity
  • Polymerase Chain Reaction
  • RNA-Directed DNA Polymerase
  • X Chromosome*

Substances

  • Carrier Proteins
  • Contractile Proteins
  • Filamins
  • Microfilament Proteins
  • Muscle Proteins
  • DNA
  • RNA-Directed DNA Polymerase

Associated data

  • GENBANK/X70082
  • GENBANK/X70083
  • GENBANK/X70084
  • GENBANK/X70085