Objective: To present a case of immotile cilia syndrome, a very rare cause of male infertility and to evaluate the role of the recently suggested treatment by intracytoplasmic sperm injection (ICSI).
Design: Case report.
Setting: Tertiary-care academic hospital.
Patient(s): One man with immotile cilia syndrome, showing no motile spermatozoa despite normal morphology and viability.
Intervention(s): The patient's partner underwent two cycles with IVF of the oocytes achieved by ICSI.
Main outcome measure(s): Evaluation of ICSI procedure in cases of immotile cilia syndrome.
Result(s): Thirty-three percent of the oocytes were fertilized and subsequently divided enabling ET in both cycles.
Conclusion(s): Intracytoplasmic sperm injection seems to represent a promising approach to the problem of infertility in men with immotile cilia syndrome.