Identification, characterization, and precise mapping of a human gene encoding a novel membrane-spanning protein from the 22q11 region deleted in velo-cardio-facial syndrome

Genomics. 1997 Jun 1;42(2):245-51. doi: 10.1006/geno.1997.4734.

Abstract

Velo-cardio-facial syndrome (VCFS) and DiGeorge syndrome (DGS) are characterized by a wide spectrum of phenotypes including cleft palate, conotruncal heart defects, and facial dysmorphology. Hemizygosity for a portion of chromosome 22q11 has been detected in 80-85% of VCFS/DGS patients. Using a cDNA selection protocol, we have identified a new gene, TMVCF (transmembrane protein deleted in VCFS), which maps to the deleted interval. The genomic locus is positioned between polymorphic markers D22S944 and D22S941. TMVCF encodes a small protein of 219 amino acids that is predicted to contain two membrane-spanning domains. TMVCF is expressed abundantly in human adult lung, heart, and skeletal muscle, and transcripts can be detected at least as early as Day 9 of mouse development.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Abnormalities, Multiple / genetics*
  • Adult
  • Amino Acid Sequence
  • Animals
  • Base Sequence
  • Chromosome Mapping
  • Chromosomes, Human, Pair 22 / genetics*
  • Claudin-5
  • Cleft Palate / genetics
  • Cloning, Molecular
  • DNA, Complementary / genetics
  • Embryonic and Fetal Development / genetics
  • Face / abnormalities
  • Heart Defects, Congenital / genetics
  • Humans
  • Membrane Proteins / genetics*
  • Mice
  • Molecular Sequence Data
  • Sequence Deletion
  • Sequence Homology, Amino Acid
  • Syndrome

Substances

  • CLDN5 protein, human
  • Claudin-5
  • Cldn5 protein, mouse
  • DNA, Complementary
  • Membrane Proteins

Associated data

  • GENBANK/AF000959