Analysis of FMR1 and flanking microsatellite markers in normal and fragile X chromosomes in Portugal: evidence for a "protector" haplotype

Eur J Hum Genet. 1998 Sep-Oct;6(5):518-22. doi: 10.1038/sj.ejhg.5200204.

Abstract

In order to look for linkage disequilibrium between the fragile X locus and its flanking markers, we analysed the FRAXAC1 and DXS548 microsatellites in normal and fragile X individuals of Portuguese origin. We observed differences in allele and haplotype frequencies between these two samples. Four haplotypes (A-2, C-2, C-5 and D-6) accounted for 76% of all fragile X chromosomes, whereas a single haplotype (C-7) accounted for 70% of the normal population and less than 3% of the fragile X chromosomes. Among the four observed high-risk haplotypes, A-2 and D-6 had been previously reported in other studies, but C-2 and C-5 seem characteristic of Portuguese patients, as suggested by the high frequency (38%) in fragile X chromosomes and virtual absence in controls. In accordance with previous studies, a greater heterozygosity of the fragile X sample was noted when compared to that of controls. The high frequency of C-7 haplotype in the normal population and its virtual absence in the fragile X sample may reflect the existence of linkage disequilibrium between the two loci and/or selective advantage (protector effect) of this haplotype.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Fragile X Mental Retardation Protein
  • Fragile X Syndrome / genetics*
  • Genetic Markers*
  • Haplotypes*
  • Humans
  • Linkage Disequilibrium*
  • Male
  • Microsatellite Repeats
  • Nerve Tissue Proteins / genetics*
  • Portugal
  • RNA-Binding Proteins*

Substances

  • FMR1 protein, human
  • Genetic Markers
  • Nerve Tissue Proteins
  • RNA-Binding Proteins
  • Fragile X Mental Retardation Protein