[Huntington chorea: clniical and molecular analysis in Asturian patients]

Neurologia. 1999 Jan;14(1):11-5.
[Article in Spanish]

Abstract

AIM AND PATIENTS: To analyse 38 patients with Huntington's disease from 27 families.

Results: The CAG repeat at the huntingtin gene was expanded between 40 and 72 times. The size in normal chromosomes varied from 12 to 30 repeats. We found a significantly negative correlation between the number of CAG-repeats and the age of clinical manifestations. However, age and clinical characteristics of the first symptoms were highly variable between patients with a similar size of the expanded allele. Patients who inherited the disease from their fathers showed a higher number of repeats than those who received the disease from their mothers. However, in one case of father to son transmission we observed a reduction of the number of CAG repeats.

Conclusions: These data make it difficult to use the molecular analysis for the presymptomatic diagnosis of clinical course in individuals carrying the expansion.

MeSH terms

  • Adolescent
  • Adult
  • Age of Onset
  • Aged
  • Alleles
  • Child
  • Chorea / epidemiology
  • Chorea / etiology
  • Dementia / epidemiology
  • Dementia / etiology
  • Diagnosis, Differential
  • Female
  • Genomic Imprinting
  • Humans
  • Huntingtin Protein
  • Huntington Disease / diagnosis
  • Huntington Disease / epidemiology
  • Huntington Disease / genetics*
  • Huntington Disease / pathology
  • Male
  • Mental Disorders / epidemiology
  • Mental Disorders / etiology
  • Middle Aged
  • Mood Disorders / epidemiology
  • Mood Disorders / etiology
  • Nerve Tissue Proteins / genetics*
  • Nuclear Proteins / genetics*
  • Spain / epidemiology
  • Trinucleotide Repeats

Substances

  • HTT protein, human
  • Huntingtin Protein
  • Nerve Tissue Proteins
  • Nuclear Proteins