Sjögren's syndrome: lymphoma predisposition coupled with a reduced frequency of t(14;18) translocations in blood lymphocytes

Mol Carcinog. 1999 Mar;24(3):226-31. doi: 10.1002/(sici)1098-2744(199903)24:3<226::aid-mc9>3.0.co;2-6.

Abstract

Sjögren's syndrome (SS) is a systemic autoimmune disorder with a strong tumor predisposition (a 44-fold elevated incidence of non-Hodgkin's lymphoma has been reported). By polymerase chain reaction analysis of t(14;18), a key lymphomagenic event in peripheral blood lymphocytes, we found a lower frequency in a subset of 12 SS patients positive for SS-A/SS-B autoantibodies than in 21 healthy subjects and 20 SS patients lacking these SS marker autoantibodies (P < 0.001). All 14 mutants sequenced displayed signs typical of V(D)J recombinase activity. This perplexing result of a low rate of t(14;18) in a population strongly predisposed to t(14;18)-associated tumor development may be explained by a constitutive deficiency in V(D)J recombinase leading to autoimmunity and increased lymphoproliferation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Antibodies, Antinuclear / analysis
  • Autoimmune Diseases / genetics*
  • Autoimmunity / genetics
  • B-Lymphocytes / enzymology
  • B-Lymphocytes / pathology*
  • Base Sequence
  • Chromosomes, Human, Pair 14 / genetics
  • Chromosomes, Human, Pair 14 / ultrastructure*
  • Chromosomes, Human, Pair 18 / genetics
  • Chromosomes, Human, Pair 18 / ultrastructure*
  • DNA Nucleotidyltransferases / deficiency
  • Genes, Immunoglobulin
  • Genes, bcl-2
  • Genetic Predisposition to Disease
  • Humans
  • Immunoglobulin Heavy Chains / genetics
  • Lymphoma, Non-Hodgkin / genetics*
  • Molecular Sequence Data
  • Polymerase Chain Reaction
  • Sjogren's Syndrome / genetics*
  • Translocation, Genetic*
  • VDJ Recombinases

Substances

  • Antibodies, Antinuclear
  • Immunoglobulin Heavy Chains
  • DNA Nucleotidyltransferases
  • VDJ Recombinases