Treatment of mesenteric desmoid tumours with the anti-oestrogenic agent toremifene: case histories and an overview of the literature

Eur J Gastroenterol Hepatol. 1999 Oct;11(10):1179-83. doi: 10.1097/00042737-199910000-00018.

Abstract

Desmoid tumours are histologically benign but due to their infiltration and compression of surrounding structures potentially life-threatening fibromatous lesions of unknown aetiology. The annual incidence rate is 2-4 per million people. The mesenteric variant constitutes about 10% of all desmoid tumours, although in familial adenomatous polyposis (FAP) patients this may be up to 70%. Due to the small number of patients with mesenteric desmoids the therapy is mainly empirical. This report describes the rationale as well as the value of the short- and long-term treatment (up to 6 years) with the anti-oestrogenic agent toremifene in combination with sulindac in two patients suffering from such a mesenteric desmoid tumour. These patients did not respond to sulindac alone and previous treatment with tamoxifen together with this non-steroidal anti-inflammatory drug had also failed. An overview of the literature on the management of these dismal tumours is presented.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adult
  • Anti-Inflammatory Agents, Non-Steroidal / therapeutic use
  • Female
  • Fibromatosis, Abdominal / diagnostic imaging
  • Fibromatosis, Abdominal / drug therapy*
  • Humans
  • Male
  • Mesentery / pathology*
  • Middle Aged
  • Remission Induction
  • Selective Estrogen Receptor Modulators / therapeutic use*
  • Sulindac / therapeutic use
  • Tomography, X-Ray Computed
  • Toremifene / therapeutic use*

Substances

  • Anti-Inflammatory Agents, Non-Steroidal
  • Selective Estrogen Receptor Modulators
  • Sulindac
  • Toremifene