Partial duplication of the long arm of chromosome 15: confirmation of a causative role in craniosynostosis and definition of a 15q25-qter trisomy syndrome

Am J Med Genet. 1999 Dec 22;87(5):391-4. doi: 10.1002/(sici)1096-8628(19991222)87:5<391::aid-ajmg4>3.0.co;2-o.

Abstract

A syndrome of mental retardation and multiple congenital anomalies, including craniosynostosis and overgrowth, was observed in two related individuals from a large kindred. Both of them carried a 15q25.1-qter trisomy associated with a subtle 13qter monosomy resulting from unbalanced segregation of a familial t(13;15)(q34;q25.1) translocation. Reportedly, a further individual in this kindred has the same condition. The present report confirms previous claims that gene(s) in the distal 15q region play a role in suture formation. At the same time it adds new data to the delineation of a 15q25-qter trisomy syndrome.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Adult
  • Chromosome Banding
  • Chromosomes, Human, Pair 13
  • Chromosomes, Human, Pair 15*
  • Craniosynostoses / genetics*
  • Dermatoglyphics
  • Developmental Disabilities / genetics
  • Facies
  • Female
  • Gene Duplication*
  • Humans
  • In Situ Hybridization, Fluorescence
  • Intellectual Disability / genetics
  • Karyotyping
  • Male
  • Pedigree
  • Syndrome
  • Translocation, Genetic*
  • Trisomy*