Ataxia-pancytopenia syndrome

Am J Med Genet. 2000 Jan 31;90(3):252-4. doi: 10.1002/(sici)1096-8628(20000131)90:3<252::aid-ajmg14>3.3.co;2-m.

Abstract

We report on a Mexican girl who developed cerebellar ataxia at age 3 years and pancytopenia at age 13 years. Cerebral computed tomography scan and magnetic resonance imaging showed evidence of severe cerebellar atrophy. Telangiectasias were not present; immunoglobulins and alpha-fetoprotein levels were normal. Cytogenetic studies showed no evidence of spontaneous chromosome aberrations, a normal rate of diepoxybutane (DEB) and mitomycin C (MMC)-induced chromosome aberrations, but an increased response to bleomycin. The phenotype support the diagnosis of ataxia-pancytopenia syndrome, although monosomy of chromosome 7 was not found in bone marrow. The cytogenetic studies suggest that this may be a chromosomal instability disorder.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Ataxia Telangiectasia / diagnosis
  • Cerebellar Ataxia / diagnosis
  • Cerebellar Ataxia / genetics
  • Cerebellar Ataxia / pathology*
  • Diagnosis, Differential
  • Fanconi Anemia / diagnosis
  • Female
  • Humans
  • Karyotyping
  • Pancytopenia / diagnosis
  • Pancytopenia / genetics
  • Pancytopenia / pathology*
  • Syndrome