Ebstein's anomaly with coarctation of the aorta. An unusual association

Arq Bras Cardiol. 1999 Aug;73(2):219-24. doi: 10.1590/s0066-782x1999000800010.
[Article in English, Portuguese]

Abstract

Ebstein's anomaly with coarctation of the aorta is an extremely unusual condition. In this report, the clinical and surgical features of 3 male patients, aged 7 months, 4 years and 14 years, are discussed. All patients were in situs solitus. The first 2 patients had atrioventricular and ventriculoarterial discordance and progressed to heart failure in the neonatal period. The third had atrioventricular and ventriculoarterial concordance, as well as Wolf-Parkinson-White syndrome, with frequent episodes of paroxysmal tachycardia. The 3 patients underwent surgery for correction of the coarctation of the aorta. The patient with atrioventricular and ventriculoarterial concordance underwent tricuspid valvuloplasty using a DeVega-like technique. In addition, ablation of 2 anomalous pathways (Kent bundle), which were detected by the electrophysiologic study, was also subsequently performed. The 3 patients showed a good postoperative outcome for 2 years, although, in those with discordance, the surgical procedure did not influence the dysplasia of the tricuspid valve, because this valve showed light to moderate dysfunction.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Aortic Coarctation / complications*
  • Aortic Coarctation / diagnosis
  • Aortic Coarctation / surgery
  • Child, Preschool
  • Ebstein Anomaly / complications*
  • Ebstein Anomaly / diagnosis
  • Electrocardiography
  • Heart Valve Diseases / diagnosis
  • Heart Valve Diseases / surgery
  • Humans
  • Infant
  • Male
  • Tricuspid Valve / surgery