Ovarian mucinous cystadenocarcinoma as a cause of Zollinger-Ellison syndrome: report of a case and review of the literature

Am J Gastroenterol. 2000 May;95(5):1348-51. doi: 10.1111/j.1572-0241.2000.01096.x.

Abstract

Gastrin producing ovarian tumor is a rare cause of the Zollinger-Ellison syndrome. We report the case of an ovarian carcinoma showing increased plasma gastrin concentration. A 60-yr-old woman presented with epigastric pain and diarrhea. Physical examination showed a large mass in the lower abdomen. Computed tomography revealed a large multilocular ovarian cyst. Upper gastrointestinal endoscopy examination showed multiple ulcerations of the stomach and duodenum. The plasma gastrin level was 1500 pg/ml. No tumors were found in the pancreas and duodenum, and salpingo-oophorectomy was performed. Histologic examination revealed a mucinous tumor of borderline malignant potential. Immunoperoxidase studies for gastrin showed many gastrin-producing cells within the epithelium of the tumor. There have been 11 cases (including our patient) of gastrin-producing ovarian tumor reported in the literature. We review here the relevant literature. Although ovarian gastrinoma is extremely rare, it should be considered as a possible cause of the Zollinger-Ellison syndrome in women.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adenocarcinoma, Mucinous / complications*
  • Adenocarcinoma, Mucinous / metabolism
  • Female
  • Gastrins / metabolism
  • Hormones, Ectopic / metabolism
  • Humans
  • Middle Aged
  • Ovarian Neoplasms / complications*
  • Ovarian Neoplasms / metabolism
  • Zollinger-Ellison Syndrome / etiology*

Substances

  • Gastrins
  • Hormones, Ectopic