A Japanese child with Senior-Loken syndrome

Jpn J Ophthalmol. 2001 Nov-Dec;45(6):636-9. doi: 10.1016/s0021-5155(01)00424-5.

Abstract

Background: Senior-Loken syndrome is a rare disease that combines familial juvenile nephronophthisis with retinitis pigmentosa. We describe the clinical features of a Japanese patient with Senior-Loken syndrome emphasizing the importance of the ophthalmic findings in determining a correct diagnosis.

Case: A 6-year-old Japanese girl had anemia, mental retardation, and poor vision.

Observations: Fundus examination and electroretinography revealed that the patient had retinitis pigmentosa. A subsequent percutaneous renal biopsy disclosed chronic tubulointerstitial nephritis.

Conclusion: The ophthalmic findings in our patient led to the diagnosis of Senior-Loken syndrome. A careful ophthalmic examination was helpful in correctly diagnosing the syndrome.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Biopsy
  • Child
  • Chronic Disease
  • Electroretinography
  • Female
  • Fundus Oculi
  • Humans
  • Nephritis, Interstitial / diagnosis*
  • Retinitis Pigmentosa / diagnosis*
  • Syndrome