A mutational hot spot in the KCNQ4 gene responsible for autosomal dominant hearing impairment

Hum Mutat. 2002 Jul;20(1):15-9. doi: 10.1002/humu.10096.

Abstract

Several different mutations in the KCNQ4 K+ channel gene are responsible for autosomal dominant nonsyndromic hearing impairment (DFNA2). Here we describe two additional families originating from Europe and Japan with a KCNQ4 missense mutation (W276S) that was previously found in one European family. We compared the disease-associated haplotype of the three W276S-bearing families using closely linked microsatellite markers and intragenic single nucleotide polymorphisms. Differences between the haplotypes were found, excluding a single founder mutation for the families. Therefore, the W276S mutation has occurred three times independently, and most likely represents a hot spot for mutation in the KCNQ4 gene.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • DNA / chemistry
  • DNA / genetics
  • DNA Mutational Analysis
  • Family Health
  • Female
  • Genes, Dominant
  • Haplotypes
  • Hearing Loss, Sensorineural / genetics*
  • Humans
  • Japan
  • KCNQ Potassium Channels
  • Male
  • Microsatellite Repeats
  • Mutation
  • Mutation, Missense
  • Pedigree
  • Potassium Channels / genetics*
  • Potassium Channels, Voltage-Gated*

Substances

  • KCNQ Potassium Channels
  • KCNQ4 protein, human
  • Potassium Channels
  • Potassium Channels, Voltage-Gated
  • DNA