The zebrafish onecut gene hnf-6 functions in an evolutionarily conserved genetic pathway that regulates vertebrate biliary development

Dev Biol. 2004 Oct 15;274(2):245-59. doi: 10.1016/j.ydbio.2004.06.016.

Abstract

Targeted disruption of the onecut transcription factor, hnf-6, alters mammalian biliary system development. We have identified a related zebrafish cDNA expressed in the developing liver that is a functional ortholog of mammalian hnf-6. Antisense-mediated knockdown of zebrafish hnf-6 perturbs development of the intrahepatic biliary system. Knockdown of zebrafish hnf-6 alters expression of vhnf1 and the zebrafish orthologs of other mammalian genes regulated by hnf-6. Coinjection of mRNA encoding zebrafish vhnf1 rescues the biliary phenotype of hnf-6 morphants. These experiments strongly suggest that hnf-6 and vhnf1 function within an evolutionarily conserved pathway that regulates biliary development. Forced expression of either hnf-6 or vhnf1 also produces biliary phenotypes. Altered bile duct development in both loss- and gain-of-function experiments suggests that zebrafish biliary cells are sensitive to the dosage of hnf-6-mediated gene transcription.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Amino Acid Sequence
  • Animals
  • Base Sequence
  • Bile Ducts / embryology
  • Bile Ducts / ultrastructure
  • Biological Evolution*
  • DNA-Binding Proteins / genetics
  • DNA-Binding Proteins / metabolism
  • Gene Expression Regulation, Developmental
  • Hepatocyte Nuclear Factor 1-beta
  • Hepatocyte Nuclear Factor 6
  • Homeodomain Proteins / genetics*
  • Homeodomain Proteins / metabolism*
  • Humans
  • In Situ Hybridization
  • Lipid Metabolism
  • Liver / embryology*
  • Liver / metabolism
  • Liver / physiology
  • Liver / ultrastructure
  • Molecular Sequence Data
  • Oligonucleotides, Antisense / genetics
  • Oligonucleotides, Antisense / metabolism
  • Pancreas / cytology
  • Pancreas / embryology
  • Pancreas / metabolism
  • RNA, Messenger / metabolism
  • Sequence Alignment
  • Trans-Activators / genetics*
  • Trans-Activators / metabolism*
  • Transcription Factors / genetics
  • Transcription Factors / metabolism
  • Zebrafish / anatomy & histology
  • Zebrafish / embryology*
  • Zebrafish / genetics
  • Zebrafish / physiology
  • Zebrafish Proteins

Substances

  • DNA-Binding Proteins
  • HNF1B protein, human
  • Hepatocyte Nuclear Factor 6
  • Homeodomain Proteins
  • Oligonucleotides, Antisense
  • RNA, Messenger
  • Trans-Activators
  • Transcription Factors
  • Zebrafish Proteins
  • hnf1ba protein, zebrafish
  • Hepatocyte Nuclear Factor 1-beta