A human gene responsible for Zellweger syndrome that affects peroxisome assembly

Science. 1992 Feb 28;255(5048):1132-4. doi: 10.1126/science.1546315.

Abstract

The primary defect arising from Zellweger syndrome appears to be linked to impaired assembly of peroxisomes. A human complementary DNA has been cloned that complements the disease's symptoms (including defective peroxisome assembly) in fibroblasts from a patient with Zellweger syndrome. The cause of the syndrome in this patient was a point mutation that resulted in the premature termination of peroxisome assembly factor-1. The homozygous patient apparently inherited the mutation from her parents, each of whom was heterozygous for that mutation.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acid Sequence
  • Animals
  • Base Sequence
  • Cricetinae
  • DNA Mutational Analysis
  • Genes
  • Genetic Complementation Test
  • Humans
  • Membrane Proteins / genetics*
  • Microbodies / ultrastructure*
  • Molecular Sequence Data
  • Oligodeoxyribonucleotides / chemistry
  • Pedigree
  • Peroxisomal Biogenesis Factor 2
  • Polymerase Chain Reaction
  • Transfection
  • Zellweger Syndrome / genetics*

Substances

  • Membrane Proteins
  • Oligodeoxyribonucleotides
  • Peroxisomal Biogenesis Factor 2

Associated data

  • GENBANK/M86852