Trisomy 1q43 syndrome: a consistent phenotype with macrocephaly, characteristic face, developmental delay and cardiac anomalies

Genet Couns. 2004;15(4):449-53.

Abstract

Trisomy 1q43 syndrome: a consistent phenotype with macrocephaly, characteristic face, developmental delay and cardiac anomalies: Patients with trisomy (1)(q42-qter) present with psychomotor retardation, macrocephaly, occasional presence of facial capillary naevi, cardio-vascular anomalies and small size for gestational age. We report on a girl with the same pattern of malformations, who has pure trisomy 1 q43: duplication of the region (1) (q43) and the translocation of the terminal region of the other chromosome 1 to the derivative 1, narrowing down the critical region for the characteristic traits of severe developmental delay, macrocephaly and congenital cardiac malformations.

Publication types

  • Case Reports

MeSH terms

  • Atrophy / pathology
  • Brain / pathology
  • Child, Preschool
  • Chromosomes, Human, Pair 1 / genetics*
  • Craniofacial Abnormalities / complications
  • Craniofacial Abnormalities / genetics*
  • Female
  • Gene Duplication
  • Heart Defects, Congenital / complications
  • Heart Defects, Congenital / genetics*
  • Humans
  • In Situ Hybridization, Fluorescence
  • Infant, Newborn
  • Intellectual Disability / complications
  • Intellectual Disability / genetics*
  • Karyotyping
  • Magnetic Resonance Imaging
  • Phenotype
  • Psychomotor Disorders / complications
  • Psychomotor Disorders / diagnosis
  • Trisomy / genetics*