[Molecular diagnosis on indication of maturity onset diabetes of the young; results from 184 patients]

Ned Tijdschr Geneeskd. 2005 Jan 15;149(3):139-43.
[Article in Dutch]

Abstract

Objective: To describe the results of mutation analysis of the genes involved in maturity onset diabetes of the young (MODY) types 1-3.

Design: Descriptive.

Method: In the period July 2000-October 2003 the DNA from 184 possible MODY patients was analysed for the presence of mutations of the genes involved in MODY types 1, 2 and 3. The patients fulfilled at least one of the following criteria: diabetes mellitus had been diagnosed before the age of 25, or at least before the age of 40, there was a family history of diabetes mellitus at an early age, there were no characteristics to indicate diabetes mellitus type 1 or 2.

Results: In the blood of 65 patients (35%) a pathogenic gene mutation was found. A total of 45 patients had a mutation in the HNF-1alpha-gene (which is linked to MODY3), 11 in the glucokinase gene (MODY2) and 9 in the HNF-4alpha-gene (MODY1). Of all the HNF-1alpha-gene mutations, the insertion of a C in codon 291 was the most frequently seen (in 11 families). A mutation in exon 9 of the HNF-1alpha-gene was also shown in 9 apparently non-related families, which probably was a founder mutation.

Conclusion: The MODY subtype was found in one third of the selected patients. This diagnosis may have implications in the clinical management of the patient.

Publication types

  • English Abstract
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Age of Onset
  • DNA-Binding Proteins / genetics*
  • Diabetes Mellitus, Type 2 / diagnosis
  • Diabetes Mellitus, Type 2 / genetics*
  • Female
  • Glucokinase / genetics*
  • Hepatocyte Nuclear Factor 1
  • Hepatocyte Nuclear Factor 1-alpha
  • Hepatocyte Nuclear Factor 4
  • Humans
  • Male
  • Mutation
  • Nuclear Proteins / genetics*
  • Pedigree
  • Phosphoproteins / genetics*
  • Transcription Factors / genetics*

Substances

  • DNA-Binding Proteins
  • HNF1A protein, human
  • HNF4A protein, human
  • Hepatocyte Nuclear Factor 1-alpha
  • Hepatocyte Nuclear Factor 4
  • Nuclear Proteins
  • Phosphoproteins
  • Transcription Factors
  • Hepatocyte Nuclear Factor 1
  • Glucokinase