Moyamoya syndrome with intraventricular hemorrhage in an adult with factor V Leiden mutation

Arch Neurol. 2005 Jul;62(7):1144-6. doi: 10.1001/archneur.62.7.1144.

Abstract

Objective: To report a case of proximal occlusion of 2 major cerebral vessels associated with moyamoya network circulation that manifested by spontaneous intraventricular hemorrhage.

Design: Case report.

Patient and results: A 36-year-old Syrian man presented with symptoms of sudden-onset headache, neck stiffness, and confusion. The computed tomography scan of his brain showed intraventricular bleeding, and the subsequent 4 vessel angiographies revealed occlusion of the left middle and anterior cerebral arteries with moyamoya appearance in the terminal branches. The coagulation profile showed the presence of heterozygous factor V Leiden mutation. The patient was treated conservatively until resolution of his blood clot, and later he was started on oral anticoagulation.

Conclusion: Factor V Leiden mutation may cause large cerebral vessel occlusion with moyamoya syndrome in adults.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Anticoagulants / therapeutic use
  • Cerebral Angiography
  • Factor V / genetics*
  • Humans
  • Intracranial Hemorrhages / etiology*
  • Male
  • Moyamoya Disease / complications*
  • Moyamoya Disease / pathology*
  • Tomography, X-Ray Computed

Substances

  • Anticoagulants
  • factor V Leiden
  • Factor V