Missense mutations outside the catalytic domain of the ABO glycosyltransferase can cause weak blood group A and B phenotypes

Transfusion. 2005 Oct;45(10):1663-9. doi: 10.1111/j.1537-2995.2005.00558.x.

Abstract

Background: Only little is known about the impact of amino acid substitutions outside an enzyme's active site on A and B transferase activity.

Study design and methods: A panel of blood group A- and B-specific plasmids containing the six known missense mutations of the coding sequence upstream of exon 6 of the ABO gene were constructed. HeLa cells were used to transfect ABO expression plasmids.

Results: Expression of ABO variants containing single or multiple missense mutations in HeLa cells resulted in a significant decrease in the percentage of antigen-expressing cells (up to 29%) and in mean fluorescence intensity (MFI; up to 50%) compared to transfection with ABO*A101 or ABO*B101. Coexpression of the respective antithetical wild-type construct (ABO*A101 and ABO*B101, respectively) further reduced cell surface expression of variant ABO constructs in regard to the percentage of expressing cells (up to 53% decrease) and MFI (up to 59% decrease).

Conclusion: Weak A and B subgroups can arise from transferases with amino acid changes in the N-terminal domain, particularly in AB phenotypes, where normal A1 or B1 glycosyltransferases compete for the same substrates.

Publication types

  • Comparative Study

MeSH terms

  • ABO Blood-Group System / immunology
  • ABO Blood-Group System / metabolism*
  • Alleles
  • Amino Acid Substitution*
  • Codon / genetics
  • Exons / genetics
  • Galactosyltransferases / chemistry
  • Galactosyltransferases / genetics*
  • Galactosyltransferases / immunology
  • Galactosyltransferases / metabolism
  • HeLa Cells
  • Humans
  • Models, Molecular
  • Mutation, Missense*
  • N-Acetylgalactosaminyltransferases / chemistry
  • N-Acetylgalactosaminyltransferases / genetics*
  • N-Acetylgalactosaminyltransferases / immunology
  • N-Acetylgalactosaminyltransferases / metabolism
  • Phenotype
  • Protein Conformation
  • Protein Structure, Tertiary
  • Recombinant Fusion Proteins / physiology
  • Transfection

Substances

  • ABO Blood-Group System
  • Codon
  • Recombinant Fusion Proteins
  • Galactosyltransferases
  • N-Acetylgalactosaminyltransferases
  • UDPgalactosamine-galactose acetylgalactosaminyltransferase
  • blood-group-substance alpha-D-galactosyltransferase