Recurrent polyradiculoneuropathy and PMP22 defects

J Chin Med Assoc. 2005 Nov;68(11):513-6. doi: 10.1016/S1726-4901(09)70085-1.

Abstract

Background: Although immunologic factors play an important role in the pathogenesis of the inflammatory neuropathies, the mechanisms of recurrent episodes of Guillain-Barré syndrome (GBS) and chronic relapsing polyneuropathies (CRP) are not known. Hereditary neuropathy with liability to pressure palsy (HNPP) is an inherited disease caused by a deletion or point mutation in the peripheral myelin protein 22 (PMP22) gene, which may manifest as a recurrent polyradiculoneuropathy. This study tried to elucidate the relationship between PMP22 and recurrent GBS and CRP.

Methods: Between 1993 and 2003, we saw 114 patients with polyradiculoneuropathies or their variants. Only 4 patients had recurrent episodes: 2 had recurrent GBS and 2 had CRP. We analyzed the PMP22 gene to determine its genetic role in these 4 patients. Genomic DNA was extracted from peripheral lymphocytes of all 4 patients using a previously described procedure, and molecular detection of PMP22 deletion was performed.

Results: The results showed no duplication, deletion or point mutation in the PMP22 gene.

Conclusion: PMP22 gene deletion did not play a role in our patients with recurrent GBS and CRP.

MeSH terms

  • Adult
  • Female
  • Gene Deletion
  • Humans
  • Male
  • Middle Aged
  • Myelin Proteins / genetics*
  • Point Mutation
  • Polyradiculoneuropathy / genetics*
  • Recurrence

Substances

  • Myelin Proteins
  • PMP22 protein, human