Acute retinal necrosis diagnosed in a child with chronic panuveitis

Graefes Arch Clin Exp Ophthalmol. 2006 Sep;244(9):1206-8. doi: 10.1007/s00417-005-0233-y. Epub 2006 Jan 13.

Abstract

Background: To report the case of an immunocompetent child with herpes simplex virus-2 (HSV-2) acute retinal necrosis (ARN) syndrome, who was considered to have an idiopathic unilateral panuveitis sensitive to steroid treatment.

Methods: Polymerase chain reaction for detection of viral DNA was applied to ocular fluids and in situ hybridization was performed on a retinal sample. HSV serology was performed using the ELISA and Western blot techniques, and an in-house indirect immunofluorescence technique.

Results: In addition to the atypical clinical presentation, the serological assays for HSV were negative using ELISA at the time of diagnosis of ARN and 1 year after. HSV2 infection was confirmed by using polymerase chain reaction of aqueous humor specimen and in situ hybridization of a retinal biopsy. Retrospective analysis with the Western blot technique detected low titers of anti-HSV antibodies, when the sera were concentrated 5-fold.

Conclusion: Herpes virus infections must be investigated in children with posterior or panuveitis. PCR analysis is a reliable technique for diagnosis. This case emphasizes that clinical presentation can be atypical and that a negative viral serology does not exclude an acute or a past herpetic infection.

Publication types

  • Case Reports

MeSH terms

  • Acyclovir / analogs & derivatives
  • Acyclovir / therapeutic use
  • Antibodies, Viral / blood
  • Antiviral Agents / therapeutic use
  • Aqueous Humor / virology
  • Child, Preschool
  • Chronic Disease
  • DNA, Viral / analysis
  • Enzyme-Linked Immunosorbent Assay
  • Eye Infections, Viral / diagnosis
  • Eye Infections, Viral / drug therapy
  • Eye Infections, Viral / virology*
  • Herpes Simplex / diagnosis
  • Herpes Simplex / drug therapy
  • Herpes Simplex / virology*
  • Herpesvirus 2, Human / isolation & purification*
  • Humans
  • In Situ Hybridization
  • Male
  • Panuveitis / diagnosis
  • Panuveitis / drug therapy
  • Panuveitis / virology*
  • Polymerase Chain Reaction
  • Retinal Necrosis Syndrome, Acute / diagnosis
  • Retinal Necrosis Syndrome, Acute / drug therapy
  • Retinal Necrosis Syndrome, Acute / virology*
  • Valacyclovir
  • Valine / analogs & derivatives
  • Valine / therapeutic use

Substances

  • Antibodies, Viral
  • Antiviral Agents
  • DNA, Viral
  • Valine
  • Valacyclovir
  • Acyclovir