Rett syndrome: exclusion mapping following the hypothesis of germinal mosaicism for new X-linked mutations

Hum Genet. 1991 Apr;86(6):604-6. doi: 10.1007/BF00201549.

Abstract

The hypothesis of germinal mosaicism in the unaffected mother of two half-sisters affected with Rett syndrome is postulated to explain the unusual recurrence of this genetic disorder affecting only females (1/10,000); it might be caused by new X-linked mutations with lethality in male fetuses. The analysis of 34 X-linked restriction fragment length polymorphisms (RFLPs) in these two affected females and in their unaffected mother and half-brother, together with the reconstruction of phase for 15 informative RFLPs in somatic cell hybrids retaining a single X chromosome from each female, has made it possible to exclude some regions of the X chromosome as possible sites of the mutation(s) causing Rett syndrome.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Cell Line
  • Chromosome Mapping
  • Female
  • Genetic Linkage*
  • Humans
  • Male
  • Mosaicism / genetics*
  • Mutation*
  • Pedigree
  • Polymorphism, Restriction Fragment Length
  • Rett Syndrome / genetics*
  • X Chromosome*