Partial cerebellar hypoplasia in a patient with Prader-Willi syndrome

Acta Paediatr. 2006 Jul;95(7):861-3. doi: 10.1080/08035250500527307.

Abstract

We report a 3-y-old male infant with Prader-Willi syndrome (PWS) caused by a de novo interstitial deletion of 15q11-q13. Additional features included a right cerebellar hemisphere hypoplasia. The extent of deletion was determined by FISH analysis using an SNRPN PW/AS probe that maps in the PWS/AS critical region (CR) and with specific 15q BACs. We unravelled an interstitial 15q11.2-q13.1 deletion spanning about 3 Mb.

Conclusion: To date only a few other PWS patients--including autopsy cases--with CNS structural anomalies have been described. Our case report adds knowledge to the issue of brain involvement in Prader-Willi syndrome. Further MRI studies of PWS patients will be helpful to clarify a correlation between PWS and brain abnormalities.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Cerebellum / abnormalities*
  • Cerebellum / pathology
  • Chromosomes, Artificial, Bacterial
  • Chromosomes, Human, Pair 19*
  • Humans
  • Infant
  • Magnetic Resonance Imaging
  • Male
  • Prader-Willi Syndrome / genetics
  • Prader-Willi Syndrome / pathology*