[A compound heterozygote family of familial hypercholesterolemia due to new mutations]

Zhonghua Nei Ke Za Zhi. 2006 Sep;45(9):725-9.
[Article in Chinese]

Abstract

Objective: To investigate the molecular diagnosis method and possible molecular mechanism of the etiology of a hereditary genetic hypercholesterolemia family by scanning and analyzing the related genes of hereditary hypercholesterolemia in a clinically diagnosed proband and his family members.

Methods: Molecular diagnosis was performed with PCR and then DNA sequencing of the promoter and 18 exons of low-density lipoprotein receptor (LDLR) gene and 3500 - 3531 fragment of apolipoprotein B-100 gene was carried out. The sequencing results were compared with the normal nucleotide sequence queried from the GeneBank database to discover the mutations.

Results: Familial defective apolipoprotein B-100 was excluded, as no mutation was detected in the apolipoprotein B 3500 - 3531 fragment. Two new point mutations were detected in the exon 4 of the proband's LDLR gene, they were heterozygous 685delA (Del A at 685) and 386A > G. The sequencing in his parents and other family members showed that the two mutations were paternal origin (685delA) and maternal origin (386A > G) respectively and should be located in different alleles of the proband.

Conclusion: Molecular diagnosis in the family shows that the proband is a compound heterozygote and the newly detected LDLR gene mutations of 685delA and 386A > G are the possible molecular etiological basis of the disease in this family.

Publication types

  • English Abstract

MeSH terms

  • Age of Onset
  • Child
  • DNA Mutational Analysis
  • Heterozygote*
  • Humans
  • Hyperlipoproteinemia Type II / genetics*
  • Male
  • Pedigree
  • Point Mutation
  • Promoter Regions, Genetic
  • Receptors, LDL / genetics*

Substances

  • Receptors, LDL