Clinicopathological differentiation between sclerosing cholangitis with autoimmune pancreatitis and primary sclerosing cholangitis

J Gastroenterol. 2007 Jul;42(7):550-9. doi: 10.1007/s00535-007-2038-8. Epub 2007 Jul 25.

Abstract

Background: The present study was undertaken to identify the clinicopathological differences between sclerosing cholangitis with autoimmune pancreatitis (SC-AIP) and primary sclerosing cholangitis (PSC).

Methods: We retrospectively compared the clinical, cholangiographic, and liver biopsy findings between 24 cases of PSC and 24 cases of SC-AIP.

Results: Patient age at the time of diagnosis was significantly lower in the PSC group than in the SC-AIP group. The peripheral blood eosinophil count was significantly higher in the PSC group than in the SC-AIP group, but the serum IgG4 level was significantly higher in the SC-AIP group. Cholangiography revealed band-like strictures, beaded appearance, and pruned-tree appearance significantly more frequently in PSC, whereas segmental strictures and strictures of the distal third of the common bile duct were significantly more common in SC-AIP. Liver biopsy revealed fibrous obliterative cholangitis only in the PSC specimens. No advanced fibrous change corresponding to Ludwig's stages 3 and 4 was observed in any of the SC-AIP specimens. IgG4-positive plasma cell infiltration of the liver was significantly more severe in SC-AIP than in PSC. Subsequent cholangiography showed no improvement in any of the PSC cases, but all SC-AIP patients responded to steroid therapy, and improvement in the strictures was observed cholangio-graphically.

Conclusions: Based on the differences between the patients' ages and blood chemistry, cholangiographic, and liver biopsy findings, SC-AIP should be differentiated from PSC.

MeSH terms

  • Adult
  • Age Factors
  • Aged
  • Autoimmune Diseases / complications
  • Autoimmune Diseases / diagnosis*
  • Autoimmune Diseases / pathology
  • Biopsy
  • Cholangiography
  • Cholangitis, Sclerosing / complications
  • Cholangitis, Sclerosing / diagnosis*
  • Cholangitis, Sclerosing / pathology
  • Diagnosis, Differential
  • Diagnostic Imaging / methods
  • Eosinophils
  • Female
  • Humans
  • Immunoglobulin G / blood
  • Immunoglobulin G / metabolism
  • Immunohistochemistry
  • Leukocyte Count
  • Liver / pathology
  • Male
  • Middle Aged
  • Pancreas / pathology
  • Pancreatitis / complications
  • Pancreatitis / diagnosis*
  • Pancreatitis / pathology
  • Retrospective Studies

Substances

  • Immunoglobulin G