[GNAS1 gene abnormality in pseudohypoparathyroidism I a]

Clin Calcium. 2007 Aug;17(8):1214-9.
[Article in Japanese]

Abstract

Pseudophypoparathyroidism (PHP) is characterized by hypocalcemia, hyperphosphatemia and elevated levels of parathyroid hormone (PTH) due to resistance to PTH. PHP type I a is caused by heterozygous inactivating mutation of the GNAS1 gene, which encodes signal transducer, Gsalpha. PHP type I a is associated with Albright's osteodystrophy (AHO). Those patients who have AHO phenotype without hormone resistance are affected by pseudopseudohypoparathyroidism.

Publication types

  • Review

MeSH terms

  • Calcitriol / therapeutic use
  • Chromogranins
  • Fibrous Dysplasia, Polyostotic / genetics
  • GTP-Binding Protein alpha Subunits, Gs / genetics*
  • Humans
  • Hydroxycholecalciferols / therapeutic use
  • Mutation*
  • Pseudohypoparathyroidism / diagnosis
  • Pseudohypoparathyroidism / drug therapy
  • Pseudohypoparathyroidism / genetics*
  • Pseudopseudohypoparathyroidism / genetics
  • Signal Transduction

Substances

  • Chromogranins
  • Hydroxycholecalciferols
  • GNAS protein, human
  • GTP-Binding Protein alpha Subunits, Gs
  • Calcitriol
  • alfacalcidol