Organic acids in aqueous humour and plasma: post mortem study in infants and diagnosis of enzymopathies

J Inherit Metab Dis. 1991;14(5):668-73. doi: 10.1007/BF01799931.

Abstract

Organic acids have been determined in aqueous humour and plasma by gas chromatography-mass spectrometry in 38 cases of infant death and 4 cases of inherited metabolic disease: one had a complex fatty-acid oxidation disorder with a large urinary excretion of adipic acid, the others had a disorder of propionate catabolism with a large urinary excretion of methylmalonic acid. In each case we found in aqueous humour the abnormal metabolite present in urine. Thus aqueous humour could be a suitable material for retrospective diagnosis of inherited metabolic diseases at autopsy in sudden infant death syndrome.

MeSH terms

  • Adipates / urine
  • Aqueous Humor / chemistry*
  • Carboxylic Acids / analysis*
  • Carboxylic Acids / blood
  • Fatty Acids / metabolism
  • Gas Chromatography-Mass Spectrometry
  • Humans
  • Infant
  • Infant, Newborn
  • Metabolism, Inborn Errors / diagnosis*
  • Methylmalonic Acid / urine
  • Propionates / metabolism
  • Retrospective Studies

Substances

  • Adipates
  • Carboxylic Acids
  • Fatty Acids
  • Propionates
  • adipic acid
  • Methylmalonic Acid
  • propionic acid