Carnitine therapy and metabolism in the disorders of propionyl-CoA metabolism studied using 1H-NMR spectroscopy

Clin Chim Acta. 1991 Dec 31;204(1-3):263-77. doi: 10.1016/0009-8981(91)90237-7.

Abstract

1H-NMR spectroscopy has been used to study metabolic perturbations in patients with disorders of propionyl-CoA metabolism during the administration of oral and intravenous L-carnitine. The administration of L-carnitine either in the form of a challenge or as a therapeutic measure resulted in an increased excretion of propionylcarnitine, consistent with the removal of accumulated intramitochondrial propionyl-CoA esters. Additionally, during the therapeutic administration of L-carnitine excretion of acetylcarnitine occurred, coincident with an improvement in clinical condition and confirming the intracellular propionyl-CoA depletion. An additional benefit from the formation of acylcarnitines may be an accompanying intracellular alkalinisation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acyl Coenzyme A / metabolism*
  • Amino Acid Metabolism, Inborn Errors / drug therapy*
  • Amino Acid Metabolism, Inborn Errors / metabolism
  • Carnitine / therapeutic use*
  • Carnitine / urine
  • Child, Preschool
  • Female
  • Gas Chromatography-Mass Spectrometry
  • Humans
  • Infant
  • Infant, Newborn
  • Kinetics
  • Magnetic Resonance Spectroscopy*
  • Male
  • Methylmalonic Acid / urine
  • Propionates / blood

Substances

  • Acyl Coenzyme A
  • Propionates
  • propionyl-coenzyme A
  • Methylmalonic Acid
  • propionic acid
  • Carnitine