Functional pulmonary atresia in a patient with neonatal Marfan syndrome caused by a c.3602G>A mutation in exon 29 of the FBN1 gene

Clin Dysmorphol. 2008 Apr;17(2):127-128. doi: 10.1097/MCD.0b013e328248b6b0.

Abstract

Neonatal Marfan syndrome is a severe form of the syndrome mostly caused by de-novo mutations in the fibrillin-1 gene. We report a newborn with neonatal Marfan syndrome and functional pulmonary atresia who died from congestive heart failure on postnatal day 22 despite treatment. He had a mutation in exon 29 of the fibrillin-1 gene at position c.3602G>A. Functional pulmonary atresia may be a life-threatening cardiovascular manifestation of neonatal Marfan syndrome.

Publication types

  • Case Reports

MeSH terms

  • Fatal Outcome
  • Fibrillin-1
  • Fibrillins
  • Heart / physiopathology
  • Heart Failure / etiology
  • Heart Failure / physiopathology
  • Humans
  • Infant, Newborn
  • Male
  • Marfan Syndrome / complications
  • Marfan Syndrome / genetics*
  • Marfan Syndrome / pathology
  • Microfilament Proteins / genetics*
  • Mutation, Missense*
  • Pulmonary Atresia / complications*
  • Pulmonary Atresia / physiopathology

Substances

  • FBN1 protein, human
  • Fibrillin-1
  • Fibrillins
  • Microfilament Proteins