A novel therapeutic paradigm to treat congenital hypothyroidism

Clin Endocrinol (Oxf). 2008 Jul;69(1):142-7. doi: 10.1111/j.1365-2265.2008.03172.x.

Abstract

Objective: To determine the effectiveness of a novel therapeutic paradigm to treat congenital hypothyroidism (CH) incorporating variable initial doses of L-T4 based on the underlying aetiology and frequent monitoring, up to 2 years of age.

Design: Retrospective cohort study.

Patients: Infants with primary CH diagnosed by newborn screening.

Measurements: Treatment with L-T4 suspension initiated at 10, 12 and 15 microg/kg/day for dyshormonogenesis, ectopia and athyreosis, respectively. Serum TSH and free T4 (FT4) levels monitored weekly during the first 4 weeks, at 6 weeks, thereafter monthly during the first 2 years. Dose changes were made to keep FT4 level in upper half of the normal range.

Results: Sixty-nine infants; 17 had dyshormonogenesis, 35 ectopia and 17 athyreosis. Seventy-eight percent of subjects normalized FT4 levels within 7 days of treatment and 100% within 14 days. TSH levels normalized in 26% of infants within 7 days and in 92% by 21 days. Supraphysiological levels of FT4 were noted in 28% of infants, for a maximum of 2 weeks. 48% infants needed one dose adjustment and 30% needed at least two in the first month. In 52 infants over the first 2 years, mean FT4 levels were consistently in the upper half of the normal range. Two or more dose adjustments every 3 months were made 57 times in the first year as compared to 19 times in the second year.

Conclusions: A variable initial dose paradigm based on aetiology with frequent testing and using T4 suspension rapidly normalizes FT4 levels without producing persistent hyperthyroxinaemia.

Publication types

  • Evaluation Study

MeSH terms

  • Algorithms*
  • Child
  • Child, Preschool
  • Cohort Studies
  • Congenital Hypothyroidism / blood
  • Congenital Hypothyroidism / diagnosis
  • Congenital Hypothyroidism / drug therapy*
  • Dose-Response Relationship, Drug
  • Drug Dosage Calculations
  • Female
  • Follow-Up Studies
  • Hormone Replacement Therapy
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Neonatal Screening
  • Retrospective Studies
  • Thyrotropin / blood
  • Thyroxine / administration & dosage*
  • Thyroxine / blood
  • Time Factors

Substances

  • Thyrotropin
  • Thyroxine