An induction gene trap screen in neural stem cells reveals an instructive function of the niche and identifies the splicing regulator sam68 as a tenascin-C-regulated target gene

Stem Cells. 2008 Sep;26(9):2321-31. doi: 10.1634/stemcells.2007-1095. Epub 2008 Jul 10.

Abstract

Neural stem cells (NSCs) reside in a niche that abounds in extracellular matrix (ECM) molecules. The ECM glycoprotein tenascin-C (Tnc) that occurs in more than 25 isoforms represents a major constituent of the privileged NSC milieu. To understand its role for NSCs, the induction gene trap technology was successfully applied to mouse embryonic NSCs, and a library of more than 500 NSC lines with independent gene trap vector integrations was established. Our pilot screen identified Sam68 as a target of Tnc signaling in NSCs. The Tnc-mediated downregulation of Sam68, which we found expressed at low levels in the niche along with Tnc, was independently confirmed on the protein level. Sam68 is a multifunctional RNA-binding protein, and its potential significance for cultured NSCs was studied by overexpression. Increased Sam68 levels caused a marked reduction in NSC cell proliferation. In addition, Sam68 is a signal-dependent regulator of alternative splicing, and its overexpression selectively increased the larger Tnc isoforms, whereas a mutated phosphorylation-deficient Sam68 variant did not. This emphasizes the importance of Sam68 for NSC biology and implicates an instructive rather than a purely permissive role for Tnc in the neural stem cell niche.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adaptor Proteins, Signal Transducing / biosynthesis*
  • Adaptor Proteins, Signal Transducing / genetics
  • Alternative Splicing
  • Animals
  • Base Sequence
  • Cell Differentiation
  • Cell Proliferation
  • Cells, Cultured
  • Mice
  • Molecular Sequence Data
  • Neurons / cytology
  • Neurons / metabolism*
  • Protein Isoforms / physiology
  • RNA-Binding Proteins / biosynthesis*
  • RNA-Binding Proteins / genetics
  • Signal Transduction
  • Stem Cells / cytology
  • Stem Cells / metabolism*
  • Tenascin / physiology*

Substances

  • Adaptor Proteins, Signal Transducing
  • Khdrbs1 protein, mouse
  • Protein Isoforms
  • RNA-Binding Proteins
  • Tenascin