Abstract
Objective:
Tumor-induced osteomalacia (TIO) is a rare condition due to phosphate wasting secondary to the release of a phosphatonin, fibroblast growth factor-23. Attempts to identify the tumor by physical examination and/or conventional imaging are sometimes unrewarding. In such cases, somatostatin receptor scintigraphy with octreotide has been successfully proposed.
Methods:
Two case reports and a review of the literature allow to demonstrate the diagnostic usefulness of octreotide and the therapeutic value of somatostatin.
Results:
Octreotide studies were positive in 79% of 24 reported TIO, including our 2 cases. In one of our patients with incomplete removal of the tumor, octreotide therapy was unable to improve hypophosphatemia, despite a decrease in fibroblast growth factor-23 levels by 30%. Similar results were achieved in most of the reported cases. Surgical procedures were effective in these cases and resulted in complete clinical and biochemical recovery.
Conclusion:
We highlight the impact of somatostatin receptor evaluation in the management of TIO.
MeSH terms
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Abdominal Neoplasms / complications
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Abdominal Neoplasms / diagnostic imaging*
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Abdominal Neoplasms / drug therapy*
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Abdominal Neoplasms / surgery
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Adult
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Angiolipoma / complications
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Angiolipoma / diagnostic imaging
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Angiolipoma / drug therapy
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Angiolipoma / surgery
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Bone Neoplasms / complications
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Bone Neoplasms / diagnostic imaging*
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Bone Neoplasms / drug therapy*
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Bone Neoplasms / surgery
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Fibroblast Growth Factor-23
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Fibroblast Growth Factors / drug effects
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Fibroblast Growth Factors / metabolism
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Foot / diagnostic imaging
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Foot / pathology
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Hip / diagnostic imaging
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Hip / pathology
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Humans
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Hypophosphatemia / drug therapy
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Hypophosphatemia / etiology
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Knee / diagnostic imaging
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Knee / pathology
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Male
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Middle Aged
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Octreotide / therapeutic use*
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Osteomalacia / diagnostic imaging*
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Osteomalacia / etiology
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Paraneoplastic Syndromes / complications
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Paraneoplastic Syndromes / diagnostic imaging
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Pelvis / diagnostic imaging
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Pelvis / pathology
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Phosphates / metabolism
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Phosphates / therapeutic use
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Radionuclide Imaging / methods
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Receptors, Somatostatin / agonists*
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Receptors, Somatostatin / antagonists & inhibitors*
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Ribs / diagnostic imaging
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Ribs / pathology
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Soft Tissue Neoplasms / complications
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Soft Tissue Neoplasms / diagnostic imaging*
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Soft Tissue Neoplasms / drug therapy*
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Soft Tissue Neoplasms / surgery
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Somatostatin / analogs & derivatives
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Somatostatin / pharmacokinetics
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Somatostatin / therapeutic use
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Whole Body Imaging
Substances
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Phosphates
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Receptors, Somatostatin
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Somatostatin
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Fibroblast Growth Factors
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Fibroblast Growth Factor-23
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pentetreotide
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Octreotide