A descriptive and prognostic study of systemic sclerosis-associated myopathies

Ann Rheum Dis. 2009 Sep;68(9):1474-7. doi: 10.1136/ard.2008.095919. Epub 2008 Dec 3.

Abstract

Objectives: To describe the clinical characteristics and muscle pathological features of patients with systemic sclerosis (SSc) and myopathy and analyse their impact on muscle outcome.

Methods: Thirty-five patients with myopathy and available muscle biopsy were restrospectively investigated from the charts of four hospital centres.

Results: Twenty-six (74%) cases had diffuse SSc. The median time from SSc diagnosis was 5 years (range 0-23) at myopathy onset. The main myopathological features were mononuclear inflammation (63%), muscle atrophy (60%), necrosis (59%), regeneration (44%), fibrosis (24%) or microangiopathy (27%). After a median follow-up of 4.4 years, 24 patients (69%) showed complete or partial muscle remission. Only histological muscle inflammation was associated with good muscle prognosis in multivariate analysis (odds ratio 44.7, 95% CI 2.8 to 704.7). Patients without muscle inflammation had a poor response to corticosteroids (38% favourable response vs 90% in patients with inflammation).

Conclusion: Muscle histopathology is critical in the therapeutic management of SSc-associated myopathy.

Publication types

  • Multicenter Study

MeSH terms

  • Adult
  • Biopsy
  • Female
  • Glucocorticoids / therapeutic use
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Muscle, Skeletal / pathology
  • Muscular Diseases / drug therapy
  • Muscular Diseases / etiology*
  • Muscular Diseases / pathology
  • Prognosis
  • Retrospective Studies
  • Scleroderma, Systemic / complications*

Substances

  • Glucocorticoids