Isolated unilateral congenital lacrimal gland agenesis presenting as filamentary keratopathy in a child

Cornea. 2009 Jan;28(1):87-8. doi: 10.1097/ICO.0b013e3181814ca9.

Abstract

Congenital lacrimal gland agenesis is extremely rare, and there are only a few cases reported in the literature. These cases involve bilateral lacrimal gland agenesis associated, in some instances, with salivary gland agenesis and abnormalities of the lacrimal puncta and canaliculi. This report, to our knowledge, presents the first documented case of unilateral lacrimal gland agenesis, resulting in unilateral filamentary keratopathy.

Publication types

  • Case Reports

MeSH terms

  • Administration, Topical
  • Child
  • Conjunctivitis / etiology
  • Eye Abnormalities / complications*
  • Eye Abnormalities / diagnostic imaging
  • Eye Abnormalities / metabolism
  • Histamine Antagonists / administration & dosage
  • Humans
  • Keratitis / drug therapy
  • Keratitis / etiology*
  • Keratitis / pathology*
  • Lacrimal Apparatus / abnormalities*
  • Lacrimal Apparatus / diagnostic imaging
  • Lacrimal Apparatus / metabolism
  • Male
  • Ophthalmic Solutions / therapeutic use
  • Steroids / administration & dosage
  • Tears / metabolism
  • Tomography, X-Ray Computed

Substances

  • Histamine Antagonists
  • Ophthalmic Solutions
  • Steroids