Molecular analysis of a patient with neurofibromatosis 1 and achondroplasia

Am J Med Genet. 1991 Jul 1;40(1):84-7. doi: 10.1002/ajmg.1320400117.

Abstract

The gene for von Recklinghausen neurofibromatosis (NF1) is on proximal 17q; the location of the gene for achondroplasia (ACH) is unknown. We have begun a molecular analysis of a patient with mental retardation, NF1 and ACH, a clinical presentation suggestive of a contiguous gene syndrome. In addition, this individual has a 47,XYY chromosome constitution. To define a possible chromosome 17 deletion, we investigated the copy number of DNA sequences linked to NF1 with conventional and pulsed-field gel electrophoresis (PFGE). We found no evidence for a deletion on chromosome 17. These results make it unlikely that this patient harbors a single deletion in the NF1 region causing both NF1 and ACH and suggest different mechanisms for the de novo occurrence of 2 autosomal dominant disorders in this individual.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Achondroplasia / complications
  • Achondroplasia / genetics*
  • Chromosomes, Human, Pair 17*
  • DNA / genetics
  • DNA / isolation & purification
  • DNA Probes
  • Genetic Carrier Screening
  • Genetic Markers
  • Homozygote
  • Humans
  • Male
  • Neurofibromatosis 1 / complications
  • Neurofibromatosis 1 / genetics*
  • Reference Values
  • Restriction Mapping

Substances

  • DNA Probes
  • Genetic Markers
  • DNA