[Hereditary ichthyosis in Tunisia: epidemiological study of 60 cases]

Tunis Med. 2008 Nov;86(11):983-6.
[Article in French]

Abstract

Background: Ichthyosis are a group of inherited keratinizing disorders. The cutaneous abnormalities may be isolated or associated with extra-cutaneous symptoms.

Aim: To report the epidemiological and clinical profiles of patients with these genodermatoses from a hospital tunisian study.

Methods: A retrospective study of all cases of ichthyosis referred during a period of 5 years to the department of dermatology of Charles Nicole's hospital of Tunis.

Results: Sixty cases of hereditary ichthyosis were seen. The sex-ratio was of 0.5. Parental consanguinity was noted in 36 patients (60%). Seventeen patients (25.7%) had a positive familial history of ichthyosis. The clinical form of ichthyosis was determined in 52 cases. The nonbullous ichthyosiform erythroderma was observed in 25 patients (41.6%). Sixty patients presented an ichthyosis vulgaris (26.6%). The other forms of ichthyosis were rarely observed : 4 cases of X-linked recessive ichthyosis, 2 cases of lamellar ichthyosis and 2 cases of bullous ichthyosiform erythroderma. Two patients were born with collodion-like membranes. Two cases presented a complex syndrome.

Conclusion: The NBIE, commonly considered as a rare form of ichthyosis, was the most frequently form seen in our study (41.6%), probably because of the high frequency of consanguineous marriages in Tunisia. The IV represents the most frequent form reported in the literature and was observed in 25% of our patients. The classification of some ichthyosis associated with other extracutaneous abnormalities (found in 2 of our patients) remains difficult.

Publication types

  • English Abstract

MeSH terms

  • Adolescent
  • Age of Onset
  • Child
  • Child, Preschool
  • Consanguinity*
  • Female
  • Genes, Recessive
  • Genetic Diseases, Inborn / epidemiology*
  • Genetic Diseases, Inborn / genetics
  • Genetic Diseases, Inborn / pathology
  • Genetic Predisposition to Disease
  • Humans
  • Ichthyosis / epidemiology*
  • Ichthyosis / genetics*
  • Ichthyosis / pathology
  • Ichthyosis, Lamellar / epidemiology
  • Ichthyosis, Lamellar / genetics
  • Incidence
  • Male
  • Pedigree
  • Retrospective Studies
  • Tunisia / epidemiology