Mutations in specific structural regions of immunoglobulin light chains are associated with free light chain levels in patients with AL amyloidosis

PLoS One. 2009;4(4):e5169. doi: 10.1371/journal.pone.0005169. Epub 2009 Apr 13.

Abstract

Background: The amyloidoses are protein misfolding diseases characterized by the deposition of amyloid that leads to cell death and tissue degeneration. In immunoglobulin light chain amyloidosis (AL), each patient has a unique monoclonal immunoglobulin light chain (LC) that forms amyloid deposits. Somatic mutations in AL LCs make these proteins less thermodynamically stable than their non-amyloidogenic counterparts, leading to misfolding and ultimately the formation of amyloid fibrils. We hypothesize that location rather than number of non-conservative mutations determines the amyloidogenicity of light chains.

Methodology/principal findings: We performed sequence alignments on the variable domain of 50 kappa and 91 lambda AL light chains and calculated the number of non-conservative mutations over total number of patients for each secondary structure element in order to identify regions that accumulate non-conservative mutations. Among patients with AL, the levels of circulating immunoglobulin free light chain varies greatly, but even patients with very low levels can have very advanced amyloid deposition.

Conclusions: Our results show that in specific secondary structure elements, there are significant differences in the number of non-conservative mutations between normal and AL sequences. AL sequences from patients with different levels of secreted light chain have distinct differences in the location of non-conservative mutations, suggesting that for patients with very low levels of light chains and advanced amyloid deposition, the location of non-conservative mutations rather than the amount of free light chain in circulation may determine the amyloidogenic propensity of light chains.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acid Sequence
  • Amyloidosis / genetics*
  • Amyloidosis / immunology*
  • Amyloidosis / pathology
  • Humans
  • Immunoglobulin Light Chains / chemistry
  • Immunoglobulin Light Chains / genetics*
  • Immunoglobulin Light Chains / metabolism*
  • Models, Molecular
  • Molecular Sequence Data
  • Multiple Myeloma / genetics
  • Multiple Myeloma / immunology
  • Mutation*
  • Protein Structure, Secondary
  • Sequence Alignment

Substances

  • Immunoglobulin Light Chains